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Clefting v5.3 ALX1 Achchuthan Shanmugasundram Tag Q3_23_promote_green was removed from gene: ALX1.
Clefting v5.3 ALX1 Sarah Leigh edited their review of gene: ALX1: Added comment: The rating of this gene has been updated to green and the mode of inheritance updated to BIALLELIC, autosomal or pseudoautosomal following NHS Genomic Medicine Service approval.; Changed mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Clefting v5.2 ALX1 Achchuthan Shanmugasundram Source Expert Review Green was added to ALX1.
Source NHS GMS was added to ALX1.
Rating Changed from Amber List (moderate evidence) to Green List (high evidence)
Clefting v4.98 ALX1 Sarah Leigh Phenotypes for gene: ALX1 were changed from ?Frontonasal dysplasia 3, 613456 to Frontonasal dysplasia 3, OMIM:613456; frontonasal dysplasia - severe microphthalmia - severe facial clefting syndrome, MONDO:0013271
Clefting v4.97 ALX1 Sarah Leigh Publications for gene: ALX1 were set to 20451171; 27324866; 26610632
Clefting v4.96 ALX1 Sarah Leigh Tag Q3_23_promote_green tag was added to gene: ALX1.
Clefting v4.96 ALX1 Sarah Leigh Classified gene: ALX1 as Amber List (moderate evidence)
Clefting v4.96 ALX1 Sarah Leigh Added comment: Comment on list classification: There is enough evidence for this gene to be rated GREEN at the next major review.
Clefting v4.96 ALX1 Sarah Leigh Gene: alx1 has been classified as Amber List (Moderate Evidence).
Clefting v4.95 ALX1 Sarah Leigh reviewed gene: ALX1: Rating: GREEN; Mode of pathogenicity: None; Publications: ; Phenotypes: ; Mode of inheritance: None
Clefting v1.59 ALX1 Eleanor Williams commented on gene: ALX1: Amber rating confirmed by Genomics England clinical team.
Clefting v1.44 ALX1 Catherine Snow Classified gene: ALX1 as Amber List (moderate evidence)
Clefting v1.44 ALX1 Catherine Snow Added comment: Comment on list classification: Changed to Amber based on Eleanor Williams review.
Clefting v1.44 ALX1 Catherine Snow Gene: alx1 has been classified as Amber List (Moderate Evidence).
Clefting v1.37 ALX1 Eleanor Williams Phenotypes for gene: ALX1 were changed from to ?Frontonasal dysplasia 3, 613456
Clefting v1.36 ALX1 Eleanor Williams Publications for gene: ALX1 were set to
Clefting v1.35 ALX1 Eleanor Williams commented on gene: ALX1: This gene is provisionally associated with ?Frontonasal dysplasia 3 (#613456) in OMIM.

PMID: 20451171 - Uz et al. (2010) - 2 families presenting with autosomal-recessive frontonasal dysplasia (FND) characterized by bilateral extreme microphthalmia, bilateral oblique facial cleft, complete cleft palate, hypertelorism, wide nasal bridge with hypoplasia of the ala nasi, and low-set, posteriorly rotated ears in two distinct families. In one family they found a three siblings were affected, and CNV analysis of the critical region showed a homozygous 3.7 Mb deletion containing the ALX1 (CART1) gene. In the second family a homozygous donor-splice-site mutation (c.531+1G > A) in the ALX1 gene was found.

PMID: 27324866 - Ullah et al 2017 - report a consanguineous family from Pakistan with four individuals presenting a milder form of Frontonasal dysplasia. Using exome sequencing, a homozygous splice acceptor site variant has been identified in the ALX1 gene. NO CLEFTING REPORTED.
Clefting v1.35 ALX1 Eleanor Williams gene: ALX1 was added
gene: ALX1 was added to Clefting. Sources: Expert list
Mode of inheritance for gene: ALX1 was set to BIALLELIC, autosomal or pseudoautosomal
Review for gene: ALX1 was set to AMBER
Added comment: Gene suggested by Andrew Wilkie, University of Oxford
Sources: Expert list