Activity

Filter

Cancel
Date Panel Item Activity
13 actions
Monogenic hearing loss v5.49 LHX3 Ida Ertmanska Tag Q1_25_ promote_green was removed from gene: LHX3.
Monogenic hearing loss v5.49 LHX3 Ida Ertmanska reviewed gene: LHX3: Rating: GREEN; Mode of pathogenicity: ; Publications: ; Phenotypes: ; Mode of inheritance:
Monogenic hearing loss v5.48 LHX3 Ida Ertmanska Source Expert Review Green was added to LHX3.
Source NHS GMS was added to LHX3.
Rating Changed from Amber List (moderate evidence) to Green List (high evidence)
Monogenic hearing loss v4.70 LHX3 Achchuthan Shanmugasundram Classified gene: LHX3 as Amber List (moderate evidence)
Monogenic hearing loss v4.70 LHX3 Achchuthan Shanmugasundram Added comment: Comment on list classification: There is sufficient evidence available for the promotion of this gene to green rating in the next GMS update.
Monogenic hearing loss v4.70 LHX3 Achchuthan Shanmugasundram Gene: lhx3 has been classified as Amber List (Moderate Evidence).
Monogenic hearing loss v4.69 LHX3 Achchuthan Shanmugasundram Mode of inheritance for gene: LHX3 was changed from to BIALLELIC, autosomal or pseudoautosomal
Monogenic hearing loss v4.68 LHX3 Achchuthan Shanmugasundram Phenotypes for gene: LHX3 were changed from to Pituitary hormone deficiency, combined, 3, OMIM:221750; sensorineural hearing loss disorder, MONDO:0020678
Monogenic hearing loss v4.67 LHX3 Achchuthan Shanmugasundram Added comment: Comment on publications: PMID:39548529 paper was identified by the Genomics England Applied Machine Learning (ML) team in a Biocuration-ML project for identifying new gene-disease associations using Natural Language Processing (NLP) and Generative AI techniques.
Monogenic hearing loss v4.67 LHX3 Achchuthan Shanmugasundram Publications for gene: LHX3 were set to
Monogenic hearing loss v4.66 LHX3 Achchuthan Shanmugasundram Tag Q1_25_ promote_green tag was added to gene: LHX3.
Monogenic hearing loss v4.66 LHX3 Achchuthan Shanmugasundram changed review comment from: PMID:10835633 reported two unrelated families with combined pituitary hormone deficiency and with biallelic LHX3 variants. The three patients from a family identified with p.Tyr116Cys variant had mild-moderate bilateral sensorineural hearing loss, while the patient with 23bp deletion had profound sensorineural deafness, when re-investigated in PMID:18407919.

PMID:18407919 reported two families with novel recessive variants in LHX3 gene. They all exhibited varying degrees of bilateral sensorineural hearing loss.

PMID:39548529 reported a group of eight patients with combined pituitary hormone deficiency-3 and all of them were identified with the same homozygous variant, c.455-2A > G. They presented with progressive sensorineural hearing deficiency ranging from moderately severe to complete loss. This variant was also associated with vestibular impairment.; to: PMID:10835633 reported two unrelated families with combined pituitary hormone deficiency and with biallelic LHX3 variants. The three patients from a family identified with p.Tyr116Cys variant had mild-moderate bilateral sensorineural hearing loss, while the patient with 23bp deletion had profound sensorineural deafness, when re-investigated in PMID:18407919.

PMID:18407919 reported two families with novel recessive variants in LHX3 gene. They all exhibited varying degrees of bilateral sensorineural hearing loss.

PMID:39548529 reported a group of eight patients with combined pituitary hormone deficiency-3 and all of them were identified with the same homozygous variant, c.455-2A > G. They presented with progressive sensorineural hearing deficiency ranging from moderately severe to complete loss. This variant is present as a founder variant in the population in Northern Sweden and was also associated with vestibular impairment.
Monogenic hearing loss v4.66 LHX3 Achchuthan Shanmugasundram reviewed gene: LHX3: Rating: GREEN; Mode of pathogenicity: None; Publications: 10835633, 18407919, 39548529; Phenotypes: Pituitary hormone deficiency, combined, 3, OMIM:221750, sensorineural hearing loss disorder, MONDO:0020678; Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal