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Intellectual disability v8.128 LINC01578 Achchuthan Shanmugasundram Tag gene-checked tag was added to gene: LINC01578.
Intellectual disability v8.119 LINC01578 Achchuthan Shanmugasundram Added comment: Comment on phenotypes: This gene has now been associated with relevant phenotype in OMIM (MIM #621012), but not yet in Gene2Phenotype.
Intellectual disability v8.119 LINC01578 Achchuthan Shanmugasundram Phenotypes for gene: LINC01578 were changed from Neurodevelopmental disorder, MONDO:0700092, CHASERR-related to Neurodevelopmental disorder with dysmorphic facies, absent speech and ambulation, and brain abnormalities, OMIM:621012
Intellectual disability v8.118 LINC01578 Achchuthan Shanmugasundram Tag locus-type-rna-long-non-coding tag was added to gene: LINC01578.
Intellectual disability v8.97 LINC01578 Sarah Leigh Tag Q3_24_promote_green was removed from gene: LINC01578.
Tag Q3_24_NHS_review was removed from gene: LINC01578.
Intellectual disability v8.97 LINC01578 Sarah Leigh commented on gene: LINC01578: The rating of this gene has been updated to green and the mode of inheritance set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted following NHS Genomic Medicine Service approval.
Intellectual disability v8.97 LINC01578 Sarah Leigh Source NHS GMS was added to LINC01578.
Source Expert Review Green was added to LINC01578.
Rating Changed from Amber List (moderate evidence) to Green List (high evidence)
Intellectual disability v8.20 LINC01578 Sarah Leigh Tag new-gene-name tag was added to gene: LINC01578.
Tag Q3_24_promote_green tag was added to gene: LINC01578.
Tag Q3_24_NHS_review tag was added to gene: LINC01578.
Intellectual disability v8.20 LINC01578 Sarah Leigh reviewed gene: LINC01578: Rating: GREEN; Mode of pathogenicity: None; Publications: ; Phenotypes: ; Mode of inheritance: MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Intellectual disability v8.20 LINC01578 Sarah Leigh Classified gene: LINC01578 as Amber List (moderate evidence)
Intellectual disability v8.20 LINC01578 Sarah Leigh Gene: linc01578 has been classified as Amber List (Moderate Evidence).
Intellectual disability v8.16 LINC01578 Zornitza Stark gene: LINC01578 was added
gene: LINC01578 was added to Intellectual disability. Sources: Literature
Mode of inheritance for gene: LINC01578 was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Publications for gene: LINC01578 were set to 39442041
Phenotypes for gene: LINC01578 were set to Neurodevelopmental disorder, MONDO:0700092, CHASERR-related
Review for gene: LINC01578 was set to GREEN
Added comment: CHASERR (aka LINC01578) encodes a human long noncoding RNA (lncRNA) adjacent to CHD2, a coding gene in which de novo loss-of-function variants cause developmental and epileptic encephalopathy. Three unrelated children reported with a syndromic, early-onset neurodevelopmental disorder, each of whom had a de novo deletion in the CHASERR locus. The children had severe encephalopathy, shared facial dysmorphisms, cortical atrophy, and cerebral hypomyelination - a phenotype that is distinct from the phenotypes of patients with CHD2 haploinsufficiency. CHASERR deletion results in increased CHD2 protein abundance in patient-derived cell lines and increased expression of the CHD2 transcript in cis, indicating bidirectional dosage sensitivity in human disease.
Sources: Literature