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Childhood onset hereditary spastic paraplegia v8.48 NFU1 Achchuthan Shanmugasundram Classified gene: NFU1 as Amber List (moderate evidence)
Childhood onset hereditary spastic paraplegia v8.48 NFU1 Achchuthan Shanmugasundram Added comment: Comment on list classification: There are patients from at least nine unrelated families reported with childhood-onset hereditary spastic paraplegia and with biallelic NFU1 variants. Hence, this gene should be promoted to green rating in the next GMS update.
Childhood onset hereditary spastic paraplegia v8.48 NFU1 Achchuthan Shanmugasundram Gene: nfu1 has been classified as Amber List (Moderate Evidence).
Childhood onset hereditary spastic paraplegia v8.47 NFU1 Achchuthan Shanmugasundram gene: NFU1 was added
gene: NFU1 was added to Childhood onset hereditary spastic paraplegia. Sources: Literature
Q2_26_promote_green tags were added to gene: NFU1.
Mode of inheritance for gene: NFU1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: NFU1 were set to 36256512
Phenotypes for gene: NFU1 were set to Spastic paraplegia 93, autosomal recessive, OMIM:620938; spastic paraplegia 93, autosomal recessive, MONDO:0975796
Review for gene: NFU1 was set to GREEN
Added comment: PMID:36256512 (2022) reported 19 affected individuals from 10 independent families with nine different biallelic NFU1 missense variants. They are associated with a spectrum of early-onset pure to complex hereditary spastic paraplegia (HSP) phenotype with a longer survival (16/19) on one end and neurodevelopmental delay with severe hypotonia (3/19) on the other. Gait acquisition was delayed due to either the insidious onset of limb spasticity in 13/19 individuals or spasticity precipitated by a deterioration in the context of a febrile illness in 4/19 individuals (Fig. 1B). The lower limb spasticity was detected at a mean age of 12 ± 6 months in the cohort. Spasticity was progressive leading to contractures in 13/19 persons and necessitating Achilles' tendon repair surgery in 4/19 affected individuals.

This gene has been associated with relevant phenotype in OMIM (MIM #620938), which was last accessed on 14 April 2026.
Sources: Literature