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Childhood onset hereditary spastic paraplegia v7.6 RINT1 Arina Puzriakova Tag Q3_24_promote_green was removed from gene: RINT1.
Childhood onset hereditary spastic paraplegia v7.6 RINT1 Arina Puzriakova reviewed gene: RINT1: Rating: GREEN; Mode of pathogenicity: ; Publications: ; Phenotypes: ; Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Childhood onset hereditary spastic paraplegia v7.5 RINT1 Arina Puzriakova Source Expert Review Green was added to RINT1.
Source NHS GMS was added to RINT1.
Rating Changed from Amber List (moderate evidence) to Green List (high evidence)
Childhood onset hereditary spastic paraplegia v6.7 RINT1 Achchuthan Shanmugasundram Classified gene: RINT1 as Amber List (moderate evidence)
Childhood onset hereditary spastic paraplegia v6.7 RINT1 Achchuthan Shanmugasundram Added comment: Comment on list classification: Three unrelated cases and functional evidence are available in support of the association of this gene with early-onset hereditary spastic paraplegia. Hence, this gene can be promoted to green rating in the next GMS update.
Childhood onset hereditary spastic paraplegia v6.7 RINT1 Achchuthan Shanmugasundram Gene: rint1 has been classified as Amber List (Moderate Evidence).
Childhood onset hereditary spastic paraplegia v6.6 RINT1 Achchuthan Shanmugasundram Phenotypes for gene: RINT1 were changed from HSP to hereditary spastic paraplegia, MONDO:0019064
Childhood onset hereditary spastic paraplegia v6.5 RINT1 Achchuthan Shanmugasundram Publications for gene: RINT1 were set to PMID: 38990652
Childhood onset hereditary spastic paraplegia v6.4 RINT1 Achchuthan Shanmugasundram Tag Q3_24_promote_green tag was added to gene: RINT1.
Childhood onset hereditary spastic paraplegia v6.4 RINT1 Achchuthan Shanmugasundram reviewed gene: RINT1: Rating: GREEN; Mode of pathogenicity: None; Publications: 37463447, 38990652; Phenotypes: hereditary spastic paraplegia, MONDO:0019064; Mode of inheritance: BIALLELIC, autosomal or pseudoautosomal
Childhood onset hereditary spastic paraplegia v6.1 RINT1 Dmitrijs Rots gene: RINT1 was added
gene: RINT1 was added to Childhood onset hereditary spastic paraplegia. Sources: Literature
Mode of inheritance for gene: RINT1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: RINT1 were set to PMID: 38990652
Phenotypes for gene: RINT1 were set to HSP
Review for gene: RINT1 was set to GREEN
Added comment: The PMID: 38990652 reports fourth case with HSP and bialellic RINT1 variants. They also note:
"The exon-intron boundaries around intron 11 may represent a mutational hotspot, given variation at c.1671+2 and c.1672-1 in all reported cases thus far."
Enough evidence for the green rating!
Sources: Literature