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Adult onset neurodegenerative disorder v7.14 SGIP1 Arina Puzriakova Added comment: Comment on publications: PMID:39332416 was identified by the Genomics England Applied Machine Learning (ML) team in a Biocuration-ML project for identifying new gene-disease associations using Natural Language Processing (NLP) and Generative AI techniques.
Adult onset neurodegenerative disorder v7.14 SGIP1 Arina Puzriakova Publications for gene: SGIP1 were set to 39332416
Adult onset neurodegenerative disorder v7.13 SGIP1 Arina Puzriakova gene: SGIP1 was added
gene: SGIP1 was added to Adult onset neurodegenerative disorder. Sources: Literature
Mode of inheritance for gene: SGIP1 was set to BIALLELIC, autosomal or pseudoautosomal
Publications for gene: SGIP1 were set to 39332416
Phenotypes for gene: SGIP1 were set to Early-onset parkinsonism
Added comment: PMID: 39332416 (2024) - consanguineous Arab family with two affected sisters who manifested young-onset parkinsonism (onset at age 19 and 22). Other features include intellectual/cognitive dysfunction, behavioral problems, and seizures (in one individual). WES revealed a homozygous missense variant (c.2080T>G (p.W694G)) in the SGIP1 gene. Functional studies in Drosophila demonstrated movement defects, synaptic transmission dysfunction, and neurodegeneration, including dopaminergic synapse loss.

Rating Red as only a single family has been reported to date.
Sources: Literature