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Paediatric or syndromic cardiomyopathy v7.92 MT-ND5 Achchuthan Shanmugasundram changed review comment from: After consultation with the clinical team, this gene is tagged for expert review by the Genomic Laboratory Hubs on the inclusion of this gene with green rating to this panel.; to: After consultation with the clinical team, this gene is tagged for expert review by the Genomic Laboratory Hubs on the inclusion of this gene with green rating on this panel.
Paediatric or syndromic cardiomyopathy v7.92 MT-ND5 Achchuthan Shanmugasundram Tag Q3_25_expert_review tag was added to gene: MT-ND5.
Tag Q3_25_NHS_review tag was added to gene: MT-ND5.
Paediatric or syndromic cardiomyopathy v7.92 MT-ND5 Achchuthan Shanmugasundram changed review comment from: After consultation with the clinical tea, this gene is tagged for expert review by the GLHs on the inclusion of this gene with green rating to this panel.; to: After consultation with the clinical team, this gene is tagged for expert review by the Genomic Laboratory Hubs on the inclusion of this gene with green rating to this panel.
Paediatric or syndromic cardiomyopathy v7.92 MT-ND5 Achchuthan Shanmugasundram commented on gene: MT-ND5: After consultation with the clinical tea, this gene is tagged for expert review by the GLHs on the inclusion of this gene with green rating to this panel.
Paediatric or syndromic cardiomyopathy v7.91 MT-ND5 Achchuthan Shanmugasundram changed review comment from: PMID:14520659 - Three unrelated patients with Leigh's syndrome were identified with m.13513G>A variant in MT-ND5 gene, of which one patient was reported with hypertrophic cardiomyopathy (HCM) among other clinical presentations.

PMID:22759514 - A 3-generation family of Han Chinese descent was reported with maternally inherited isolated HCM. They were identified with a homoplasmic m.12338T>C variant in MT-ND5 gene, leading to the replacement of initiation methionine residue to Threonine, resulting in shortening of the ND5 polypeptide by 2 amino acids.

PMID:23847141 - This study analysed the while mitochondrial DNA sequences of a cohort of 743 patients suspected of manifesting a mitochondrial disease. Nine patients were detected with a variant in MT-ND5 gene, and they presented with different combinations of phenotypes. One of four patients with m.13513G>A variants had HCM as one of the clinical features.

PMID:30587702 - A 21-year-old proband presented with biventricular hypertrophy, hyperlactacidemia, pulmonary hypertension, and decreased exercise tolerance. Skeletal muscle biopsy showed features consistent with mitochondrial myopathy. The family was identified with c.1315A>G (p.Thr439Ala) variant in MT-ND5 gene.; to: PMID:14520659 - Three unrelated patients with Leigh's syndrome were identified with m.13513G>A variant in MT-ND5 gene, of which one patient was reported with hypertrophic cardiomyopathy (HCM) among other clinical presentations.

PMID:22759514 - A 3-generation family of Han Chinese descent was reported with maternally inherited isolated HCM. They were identified with a homoplasmic m.12338T>C variant in MT-ND5 gene, leading to the replacement of initiation methionine residue to Threonine, resulting in shortening of the ND5 polypeptide by 2 amino acids.

PMID:23847141 - This study analysed the mitochondrial DNA sequences of a cohort of 743 patients suspected of manifesting a mitochondrial disease. Nine patients were detected with a variant in MT-ND5 gene, and they presented with different combinations of phenotypes. One of four patients with m.13513G>A variants had HCM as one of the clinical features.

PMID:30587702 - A 21-year-old proband presented with biventricular hypertrophy, hyperlactacidemia, pulmonary hypertension, and decreased exercise tolerance. Skeletal muscle biopsy showed features consistent with mitochondrial myopathy. The family was identified with c.1315A>G (p.Thr439Ala) variant in MT-ND5 gene.
Paediatric or syndromic cardiomyopathy v7.86 MT-ND5 Jesse Hayesmoore reviewed gene: MT-ND5: Rating: RED; Mode of pathogenicity: None; Publications: PMID: 14520659, PMID: 23847141, PMID: 37318682, PMID: 25681084, PMID: 12624137, PMID: 14730434, PMID: 36104228, PMID: 22759514, PMID: 30587702, PMID: 23628297, PMID: 19473338; Phenotypes: Leigh syndrome, LHON, MELAS; Mode of inheritance: MITOCHONDRIAL
Paediatric or syndromic cardiomyopathy v7.4 MT-ND5 Achchuthan Shanmugasundram Classified gene: MT-ND5 as Amber List (moderate evidence)
Paediatric or syndromic cardiomyopathy v7.4 MT-ND5 Achchuthan Shanmugasundram Added comment: Comment on list classification: As reviewed by Katherine Schon on R131 Hypertrophic cardiomyopathy panel, HCM is reported as one of the presenting phenotypes in several unrelated patients with variants in MT-ND5 gene.

This gene can therefore be promoted to green rating on the next GMS update.
Paediatric or syndromic cardiomyopathy v7.4 MT-ND5 Achchuthan Shanmugasundram Gene: mt-nd5 has been classified as Amber List (Moderate Evidence).
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram Tag Q2_25_ NHS_review was removed from gene: MT-ND5.
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram edited their review of gene: MT-ND5: Changed rating: GREEN
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram Deleted their comment
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram Tag Q2_25_expert_review was removed from gene: MT-ND5.
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram Entity copied from Hypertrophic cardiomyopathy v5.9
Paediatric or syndromic cardiomyopathy v7.3 MT-ND5 Achchuthan Shanmugasundram gene: MT-ND5 was added
gene: MT-ND5 was added to Paediatric or syndromic cardiomyopathy. Sources: Expert Review Amber,Literature
Q2_25_ promote_green, Q2_25_expert_review, Q2_25_ NHS_review tags were added to gene: MT-ND5.
Mode of inheritance for gene gene: MT-ND5 was set to MITOCHONDRIAL
Publications for gene: MT-ND5 were set to 14520659; 22759514; 23847141; 30587702
Phenotypes for gene: MT-ND5 were set to hypertrophic cardiomyopathy, MONDO:0005045