Deafness and congenital structural abnormalities

Gene: EVC

Red List (low evidence)

EVC (EvC ciliary complex subunit 1)
EnsemblGeneIds (GRCh38): ENSG00000072840
EnsemblGeneIds (GRCh37): ENSG00000072840
OMIM: 604831, Gene2Phenotype
EVC is in 14 panels

6 reviews

Muriel Holder (Clinical Genetics, Guy's Hospital)

Red List (low evidence)

Mode of inheritance
BOTH monoallelic and biallelic, autosomal or pseudoautosomal

Mode of pathogenicity
Other

Sarah Leigh (Genomics England Curator)

Comment when marking as ready: Associated with phenotypes in OMIM and G2P / DD. Only one variant reported in Weyers acrodental dysostosis 193530.
Created: 14 Sep 2016, 1:55 p.m.
Comment on phenotypes: Biallelic variants also reported in Ellis-van Creveld syndrome 225500
Created: 14 Sep 2016, 12:48 p.m.

Ellen McDonagh (Genomics England Curator)

Comment on list classification: Red on the Bilateral Microtia Version 1.10 panel.
Created: 12 Sep 2016, 2:56 p.m.

Ana Beleza (Bristol Regional Genetics Service)

Variants in this GENE are reported as part of current diagnostic practice

Jun Shen (Harvard Medical School)

Red List (low evidence)

Mode of inheritance
BOTH monoallelic and biallelic, autosomal or pseudoautosomal

Phenotypes
#193530:Weyers acrodental dysostosis [Short stature, mild; Prominent antihelix; Hypotelorism; Multiple frenula; Single central incisor; Conical teeth (permanent teeth); Irregular, small, or absent incisors (permanent teeth); Cleft of mandibular symphysis (infancy); Short hands; Postaxial polydactyly; Fifth finger clinodactyly; Mild brachydactyly; Postaxial polydactyly; Hypoplastic nails; Dysplastic nails]; #225500:Ellis-van Creveld syndrome [Short-limb dwarfism identifiable at birth; Average adult height, 109 to 152 cm; Normocephaly; Normal with exception of upper-lip defect; Partial cleft lip; Defect in alveolar ridge; Neonatal teeth; Hypodontia; Delayed eruption; Atrial septal defect; Single atrium; Other congenital heart defects; Narrow chest; Pectus carinatum; Short, poorly developed ribs; Epispadias; Hypospadias; Cryptorchidism; Low iliac wings; Spur-like projections at medialateral aspect of acetabula; Centrifugal shortening of limbs; Fusion of capitate and hamate; Genu valgum; Short, thickened tubular bones; Difficulty forming a fist; Postaxial polydactyly; Cone-shaped epiphyses of phalanges 2 to 5; Talipes equinovarus; Postaxial polydactyly; Nail dysplasia; Mental retardation (some); Dandy-Walker malformation]

Publications

Maria Bitner-Glindzicz (UCL)

Red List (low evidence)

MIM 604831
Created: 3 Feb 2016, 4:47 p.m.

Details

Mode of Inheritance
MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted
Sources
  • Radboud University Medical Center, Nijmegen
  • UKGTN
  • Illumina TruGenome Clinical Sequencing Services
  • Emory Genetics Laboratory
  • Expert Review Red
  • Expert list
Phenotypes
  • Bilateral Microtia
  • Weyers acrodental dysostosis
OMIM
604831
Clinvar variants
Variants in EVC
Penetrance
Complete
Panels with this gene

History Filter Activity

26 Oct 2016, Gel status: 1

panel promoted to version 1

Ellen McDonagh (Genomics England Curator)

26th Oct 2016: the panels Bilateral microtia version 1.10, Ear malformations with hearing impairment version 0.105, and familial hemifacial microsomia version 0.149 gene panels were combined to create this panel. The panel was revised due to expert review, further curation of evidence and internal clinical evaluation. Ready for promotion to version 1.

5 Oct 2016, Gel status: 1

Set Mode of Inheritance, Added New Source

Sarah Leigh (Genomics England Curator)

EVC was added to Deafness and congenital structural abnormalitiespanel. Source: Emory Genetics Laboratory EVC was added to Deafness and congenital structural abnormalitiespanel. Source: Illumina TruGenome Clinical Sequencing Services EVC was added to Deafness and congenital structural abnormalitiespanel. Source: Radboud University Medical Center, Nijmegen EVC was added to Deafness and congenital structural abnormalitiespanel. Source: UKGTN Model of inheritance for gene EVC was set to MONOALLELIC, autosomal or pseudoautosomal, NOT imprinted

5 Oct 2016, Gel status: 1

Added New Source

Sarah Leigh (Genomics England Curator)

EVC was added to Deafness and congenital structural abnormalitiespanel. Sources: Expert list,Expert Review Red

5 Oct 2016, Gel status: 0

Created

Sarah Leigh (Genomics England Curator)

EVC was created by sleigh