Genes in panel

Early onset or syndromic epilepsy

Gene: DNAJC6

Green List (high evidence)

DNAJC6 (DnaJ heat shock protein family (Hsp40) member C6)
EnsemblGeneIds (GRCh38): ENSG00000116675
EnsemblGeneIds (GRCh37): ENSG00000116675
OMIM: 608375, Gene2Phenotype
DNAJC6 is in 5 panels

6 reviews

Eleanor Williams (Genomics England Curator)

Green List (high evidence)

The rating of this gene has been updated to green and the mode of inheritance set to 'BIALLELIC, autosomal or pseudoautosomal' following NHS Genomic Medicine Service approval.
Created: 2 May 2024, 1:13 p.m. | Last Modified: 6 May 2024, 9:18 p.m.
Panel Version: 5.6

Mode of inheritance
BIALLELIC, autosomal or pseudoautosomal

Dmitrijs Rots (Children's Clinical University Hospital)

Green List (high evidence)

Ray et al. in 34175496 summarized reported cases with DNAJC6 - 6/6 studies had movement disorder and homozygous variant (nonsense, splice, frameshift and missense) and 3/6 studies had seizures reported.
Created: 11 Sep 2022, 9:39 p.m. | Last Modified: 11 Sep 2022, 9:42 p.m.
Panel Version: 2.593

Mode of inheritance
BIALLELIC, autosomal or pseudoautosomal

Publications

Rebecca Foulger (Genomics England curator)

I don't know

Review and rating collated by Tracy Lester (Oxford Medical Genetics Laboratories Oxford University Hospitals NHS Foundation Trust, 2019_02_06) on behalf of Wessex and West Midlands GLH for GMS Neurology specialist test group, for Clinical Indication R59 'Early onset or syndromic epilepsy'. Review contributors: Alison Callaway and John Taylor. Suggested gene rating: Amber.
Created: 6 Aug 2019, 8:38 p.m. | Last Modified: 6 Aug 2019, 8:38 p.m.
Panel Version: 1.189

Tracy Lester (Genetics laboratory, Oxford UK)

I don't know

Mode of inheritance
BIALLELIC, autosomal or pseudoautosomal

Phenotypes
Parkinson disease 19a juvenile-onset, 615528; Parkinson disease 19b early-onset, 615528

Publications

Sarah Leigh (Genomics England Curator)

Green List (high evidence)

Comment on list classification: There is enough evidence for this gene to be rated GREEN at the next major review.
Created: 22 Jun 2023, 4:22 p.m. | Last Modified: 22 Jun 2023, 4:22 p.m.
Panel Version: 4.62
DNAJC6 variants are associated with Parkinson disease 19b, early-onset (OMIM:615528), but not with a phenotype in Gen2Phen. At least nine variants have been reported in unrelated families. Seizures were reported in 5/9 families and dystonia was reported in 4/9 families reported (data review in PMID: 34175496.
Created: 22 Jun 2023, 4:15 p.m. | Last Modified: 22 Jun 2023, 4:15 p.m.
Panel Version: 4.61
Comment when marking as ready: Based on reviewers' comments.
Created: 11 Dec 2018, 1:18 p.m.

Zornitza Stark (Australian Genomics)

I don't know

Seizures are reported in some patients.
Created: 12 Aug 2018, 6:44 a.m.

Mode of inheritance
BIALLELIC, autosomal or pseudoautosomal

Phenotypes
Parkinson disease 19b, early-onset, MIM#615528

Variants in this GENE are reported as part of current diagnostic practice

Details

Mode of Inheritance
BIALLELIC, autosomal or pseudoautosomal
Sources
  • Expert Review Green
  • Wessex and West Midlands GLH
  • NHS GMS
  • Victorian Clinical Genetics Services
Phenotypes
  • Parkinson disease 19b, early-onset, OMIM:615528
  • Parkinson disease 19a juvenile-onset, OMIM:615528
  • juvenile onset Parkinson disease 19A, MONDO:0014231
OMIM
608375
Clinvar variants
Variants in DNAJC6
Penetrance
None
Publications
Panels with this gene

History Filter Activity

2 May 2024, Gel status: 3

Removed Tag

Achchuthan Shanmugasundram (Genomics England Curator)

Tag Q3_23_promote_green was removed from gene: DNAJC6.

2 May 2024, Gel status: 3

Added New Source, Status Update

Achchuthan Shanmugasundram (Genomics England Curator)

Source Expert Review Green was added to DNAJC6. Rating Changed from Amber List (moderate evidence) to Green List (high evidence)

22 Jun 2023, Gel status: 2

Added Tag

Sarah Leigh (Genomics England Curator)

Tag Q3_23_promote_green tag was added to gene: DNAJC6.

22 Jun 2023, Gel status: 2

Entity classified by Genomics England curator

Sarah Leigh (Genomics England Curator)

Gene: dnajc6 has been classified as Amber List (Moderate Evidence).

22 Jun 2023, Gel status: 2

Set Phenotypes

Sarah Leigh (Genomics England Curator)

Phenotypes for gene: DNAJC6 were changed from Parkinson disease 19b, early-onset, OMIM:615528; juvenile onset Parkinson disease 19A, MONDO:0014231 to Parkinson disease 19b, early-onset, OMIM:615528; Parkinson disease 19a juvenile-onset, OMIM:615528; juvenile onset Parkinson disease 19A, MONDO:0014231

22 Jun 2023, Gel status: 2

Set mode of inheritance

Sarah Leigh (Genomics England Curator)

Mode of inheritance for gene: DNAJC6 was changed from to BIALLELIC, autosomal or pseudoautosomal

22 Jun 2023, Gel status: 2

Set publications

Sarah Leigh (Genomics England Curator)

Publications for gene: DNAJC6 were set to 22563501; 23211418; 26528954; 34175496; 26703368

22 Jun 2023, Gel status: 2

Set publications

Sarah Leigh (Genomics England Curator)

Publications for gene: DNAJC6 were set to 23211418; 34175496

22 Jun 2023, Gel status: 2

Set publications

Sarah Leigh (Genomics England Curator)

Publications for gene: DNAJC6 were set to

22 Jun 2023, Gel status: 2

Set Phenotypes

Sarah Leigh (Genomics England Curator)

Phenotypes for gene: DNAJC6 were changed from to Parkinson disease 19b, early-onset, OMIM:615528; juvenile onset Parkinson disease 19A, MONDO:0014231

6 Aug 2019, Gel status: 2

Added New Source

Rebecca Foulger (Genomics England curator)

Source Wessex and West Midlands GLH was added to DNAJC6.

6 Aug 2019, Gel status: 2

Added New Source

Rebecca Foulger (Genomics England curator)

Source NHS GMS was added to DNAJC6.

11 Dec 2018, Gel status: 2

Panel promoted to version 1.0

Sarah Leigh (Genomics England Curator)

Zornitza Stark: Seizures are reported in some

11 Dec 2018, Gel status: 2

Entity classified by Genomics England curator

Sarah Leigh (Genomics England Curator)

Gene: dnajc6 has been classified as Amber List (Moderate Evidence).

25 Jun 2018, Gel status: 2

Added New Source

Sarah Leigh (Genomics England Curator)

Expert Review Amber was added to DNAJC6. Panel: Genetic Epilepsy Syndromes

25 Jun 2018, Gel status: 1

Added New Source

Sarah Leigh (Genomics England Curator)

DNAJC6 was added to Genetic Epilepsy Syndromes panel. Sources: Victorian Clinical Genetics Services

25 Jun 2018, Gel status: 1

Created

Sarah Leigh (Genomics England Curator)

DNAJC6 was created by Sarah Leigh